Forum for Nordic Dermato-Venereology Nr 3, 2018 | Page 20
Dissertation
Lichen Sclerosus and Vulvar Squamous Cell Carcinoma
M aria L agerstedt , MD
Department of Dermatology and Allergology, University of Tampere and Tampere University Hospital, Tampere, Finland.
E-mail: [email protected]
Maria Lagerstedt, MD, specializing in Dermatology and Allergology, University of Tampere and Tampere Uni-
versity Hospital, Finland, defended her PhD thesis “Vulvar lichen sclerosus, Characterization of childhood
lichen sclerosus and evaluation of novel biomarkers in the progression of lichen sclerosus to vulvar squamous
cell carcinoma” on 2 nd of February 2018. The opponent was Professor Kaisa Tasanen-Määttä from University of
Oulu, Finland and custos was Professor Erna Snellman. The thesis was supervised by Dos. Satu-Leena Laasanen
and Prof. Erna Snellman.
The theses is available at: http://urn.fi/URN:ISBN:978-952-03-0640-3
Lichen sclerosus (LS) is a chronic, scarring dermatosis typically
affecting the genital area. It can occur in women and men, and
at any age. Childhood LS is a rare entity with a few existing
previous studies. LS includes a risk for cancer (vulvar squamous
cell carcinoma [SCC]) in 3–5% of patients, but there are no
biomarkers available in clinical practise for the evaluation for
the risk of malignancy.
The aim of the dissertation study was to characterise the
features of childhood-onset LS and to evaluate the role of
biomarkers, estrogen related receptor α (ERRα) and Serpin A1
(also called alfa-1 antitrypsin), in LS and vSCC.
Childhood LS showed remarkable effects on the patients’
quality of life. Our study found an association with LS and
sleeping disorders. The risk of other autoimmune diseases
was elevated and scarring occurred in as many as one fifth
of the patients. The relief of signs and symptoms of LS was
common in puberty, but a permanent cure of the disease was
not. However, many patients dropped out of follow-up at the
time of puberty. The study concluded that the effective treat-
ment and surveillance in a professional unit can diminish the
risk of complications in lichen sclerosus patients at all ages.
The study found two novel markers in vulvar lichen sclerosus
and vulvar SCC, ERRα and Serpin A1. The prognostic value of
these markers in lichen sclerosus was not established. A novel
finding was that both of the markers seem to have a role in
development and progression of vulvar cancer.
Summary and conclusion
The current work was designed to explore the prevalence, clin-
ical picture, comorbidities and prognosis of childhood LS and
to identify immunohistochemical markers in LS and vulvar
SCC. The results of this study can be summarized as follows:
82
Fig. 1. From left to right: Prof. Kaisa Tasanen-Määttä (opponent), Prof.
Erna Snellman (supervisor), Maria Lagerstedt (responder), Dos. Satu-Lee-
na Laasanen (supervisor).
• Childhood-onset LS is rare and often misdiagnosed. LS
has a significant effect on the quality of life (QoL) of the
patients, and the 15D questionnaire seems a promising tool
for measuring the QoL in childhood-onset LS. The high
risk for other autoimmune diseases should be kept in mind
during the follow-up. To prevent the complications, the
initial therapy should be effective enough to cure clinical
symptoms and signs. Maintenance therapy and long-term
surveillance are important.
• Healthy vulvar skin expressed ERRα, ERRβ and ERRγ inde-
pendent of age or hormonal status. In LS, the expression of
ERRα was decreased independently of the clinical features,
and showed no prognostic value. ERRα staining intensity
further reduced in premalignant vulvar lesions. In vulvar
Forum for Nord Derm Ven 2018, Vol. 23, No. 3