iDentistry The Journal May 2017 | Page 14

The Journal *Dr. Seema Alice Mathew **Dr. Ravi Sankar Nutalapati Gorlin-Goltz Syndrome : Case Report and Review of a Rare Disorder Gorlin-Goltz syndrome is an autosomal dominant inherited disorder and is most uncommon, which is characterized by multiple Odontogenic Keratocysts, basal cell carcinomas, intracranial ectopic calcifications of the falx-cerebri, skeletal, dental, ophthalmic, and neurological abnormalities, and facial dysmorphism. The syndrome shows an autosomal dominant inheritance pattern with a gene mutation located on 9q22.3. It involves multi-systems comprising the triad of basal cell nevi, jaw keratocysts, and skeletal anomalies. Along with this triad it is also associated with neurological, ophthalmic, endocrine and genital manifestations. Diagnosis of the syndrome is primarily based on major and minor criteria. We have reported here a case of a 12-year-old boy presenting with one major and three minor features of Gorlin-Goltz syndrome. We presented the investigations and treatment protocol we followed. In concluding prompt and early diagnosis is necessary for better prognosis and prevents recurrence. Introduction Gorlin-Goltz syndrome is otherwise known as nevoid basal cell carcinoma (BCC) Syndrome is a rare autosomal dominant disorder with high penetrance capacity and with extreme variable expressivity. In 1894, Jarisch and White made the first descriptions of patients with this syndrome, focussing the presence of multiple basocellular car