Hearing Health Summer 2015 Issue Summer 2015 | Page 22
research
Distilling
the Data
The burgeoning field of bioinformatics allows the Hearing Restoration Project to
analyze and compare large genomics datasets and identify the best genes for
more testing. This sophisticated data analysis will help speed the way toward a
cure for hearing loss and tinnitus.
ince its launch in 2011, the Hearing Restoration
Project (HRP) is focused on identifying new
therapies that will restore inner ear hair cell function, and
hence hearing. Within the consortium, smaller research
groups engage in separate projects over the course of the
year, to move the science along more quickly.
Over the past decade my group, and the group led
by my collaborator Mark Warchol, Ph.D., have worked
to identify genes that are potential targets for drug
development or for gene therapies to cure hearing
loss. Our approach has been to determine the exact
mechanisms that some vertebrates—in our case, birds—
use to regenerate their hair cells and thus spontaneously
restore their hearing. We have been comparing this genetic
“tool kit” with the mechanisms that mammals normally
use to make hair cells.
Unlike birds, mammals cannot regenerate adult
hair cells when they are damaged, which is a leading
cause of human hearing and balance disorders. Our
working hypothesis is that birds have regeneration
mechanisms that mammals are missing—or that mammals
have developed a repressive mechanism that prevents
hair cell regeneration.
In either case, our strategy has been to get a detailed
picture of what transpires during hair cell regeneration
in birds by using cutting-edge technologies developed
during the Human Genome Project (the international
research collaboration whose goal was the complete
22 | hearing health | a publication of hearing health foundation
mapping of all the nuclear DNA in humans). These nextgeneration (NextGen) DNA sequencing methods have
allowed us to accurately measure changes in every single
gene as chick sensory hair cells regenerate.
The good news is that this gives us, for the first time,
an exquisitely detailed and accurate description of all of
the genes that are potential players in the process. The
bad news is that this is an enormous amount of
information; thousands of genes change over the course
of seven days of regeneration.
Some of these will be the crucially important—and
possibly game-changing—genes that we want to explore
in potential therapies, but most will be downstream
effects of those upstream formative events.The challenge
is to correctly identify the important causative needles in
the haystack of later consequences.
We already know some important genetic players, but
we are still far from understanding the genetic wiring of
hair cell development or regeneration. For example, after
decades of basic research, we know that certain signaling
pathways, such as those termed Notch and Wnt, are
important in specifying how hair cells develop. These
chemical signaling pathways are made of multiple protein
molecules, each of which is encoded by a single gene.
However, the Notch and Wnt pathways together
comprise fewer than 100 genes and, despite being
intensively studied for years, we do not completely
understand every nuance of how they fit together.
Photo credit: istockphoto.com/Magnilion
S
By Michael Lovett, Ph.D.