Acta Dermato-Venereologica Issue No. 97-5 97-5CompleteContent | Page 21
SHORT COMMUNICATION
Increased Serum Levels of Th2-type Cytokines and Eotaxin in Fibrillar-type Dermatitis Herpetiformis
Teruhiko MAKINO 1 , Yoko YOSHIHISA 1 , Megumi MIZAWA 1 , Kiyohiro TSUTSUI 2 , Chihiro NISHIJIMA 3 , Makoto INAOKI 3 and
Tadamichi SHIMIZU 1
1
Department of Dermatology, Graduate School of Medicine and Pharmaceutical Sciences, University of Toyama, Sugitani 2630, Toyama 930-
0194, 2 Department of Dermatology, Ishikawa Prefectural Central Hospital, Ishikawa, and 3 Department of Dermatology, National Hospital
Organization Kanazawa Medical Center, Kanazawa, Japan. E-mail: [email protected]
Accepted Dec 15, 2016; Epub ahead of print Dec 16, 2016
Dermatitis herpetiformis (DH) is a pruritic papulovesi-
cular disease that is symmetrically distributed over the
shoulders, elbows, back and knees. Immunofluorescence
has revealed granular IgA deposition in the papillary der-
mis. IgA antibodies to both epidermal transglutaminase
(eTG) and tissue transglutaminase (tTG) are usually
detected in patients with DH. DH is commonly thought
to be a cutaneous manifestation of gluten-sensitive
enteropathy (GSE) (1, 2). We refer to this condition as
“granular-type DH”. Although DH is a relatively com-
mon disease in Caucasian populations, it is rare in Japan.
Most Japanese patients with DH show unique features,
including a high frequency of fibrillar IgA deposition in
the papillary dermis, rare occurrence of GSE, absence of
the HLA-DQ2/DQ8 haplotype and rare associations with
autoimmune disease and lymphoma, although the histo-
logical findings appear to be similar to those of granular-
type DH (3, 4). Furthermore, as reported previously,
these patients appear to have IgA antibodies to eTG, but
not tTG (5). We refer to this condition as “fibrillar-type
DH”. The clinical and histological findings of typical
fibrillar-type DH are shown in Fig. S1 1 . Fibrillar-type
DH appears to be rare in Caucasian populations (6).
While the pathogenesis of DH is unclear, previous studies
have suggested that the expression of interleukin (IL)-8,
granulocyte-macrophage colony-stimulating factor (GM-
CSF) and Th2-type cytokines could be important in the
tissue infiltration process of eosinophils and neutrophils
in granular-type DH (7, 8). The present study investigated
the levels of serum cytokines and chemokines in order
to clarify their presence and activity in the pathogenesis
of fibrillar-type DH.
Table I. Characteristics of study patients with fibrillar-type dermatitis
herpetiformis
Age,
years/
Sex DIF (IgA
deposition)
73/M
41/M
81/M
65/M
78/M Fibrillar
Fibrillar
Fibrillar
Fibrillar
Fibrillar
GSE HLA-DQ2
or DQ8 IgA antibodies
to eTG (cut-off
<18 AU/ml) IgA antibodies
to tTG (cut-off
<18 AU/ml)
–
–
–
–
– n.d.
n.d.
–
–
– 114.5
47.5
58.6
95.8
70.9 3.6
8.1
1.5
0.16
0.59
DIF: direct immunofluorescence; GSE: gluten-sensitive enteropathy; n.d.: not
done; eTG: epidermal transglutaminase; tTG: tissue transglutaminase.
MATERIALS AND METHODS ( see Appendix S1 1 )
RESULTS
The study population included 5 patients with fibrillar-
type DH (mean age 67.4 years; age range 41–81 years)
in the active stage of the disease, who had not received
any treatment and in whom the development of new
lesions had been observed (Table I). The levels of IgA
antibodies against eTG were markedly increased in all
patients. However, no IgA antibodies against tTG were
detected in any of the patients. None of the patient’s
intestinal tissue specimens showed villous atrophy or
lymphocytic cell infiltration.
The serum level of interferon (IFN)-γ, a Th1-like
cytokine, was increased slightly in the patients with DH
(mean 0.414 ± 0.23; range 0.21–0.80 pg/ml) in compa-
rison with the control subjects; however, the difference
was not statistically significant. IL-12, another Th1-like
cytokine, was not detected in either the patients with DH
or the control subjects (Fig. S2a 1 ).
The patients’ serum levels of Th2-like cytokines
IL-4 (mean14.55 ± 5.3 pg/ml; range 6.84-21.71 pg/ml,
https://www.medicaljournals.se/acta/content/abstract/10.2340/00015555-2604
p < 0.005), IL-5 (mean 6.09 ± 0.99 pg/ml; range 4.84–7.49
pg/ml, p < 0.001) and IL-13 (mean 1.14 ± 0.20
30
10
pg/ml; range 0.85–1.36 pg/ml, p < 0.005) were
**
IL-5
IL-4
*
significantly increased in comparison with
25
8
the normal subjects: IL-4: mean 0.04 ± 0.09
20
6
pg/ml; range 0-0.21 pg/ml, IL-5: mean
15
4
0.55 ± 0.14 pg/ml; range 0.37–0.72 pg/ml, IL-
10
13:
mean 0.21 ± 0.09 pg/ml; range 0.08–0.29
2
5
pg/ml,
respectively (Fig. 1 and Fig. S2b 1 ).
0
0
Patient
Healthy
Patient
Healthy
The serum IL-8 level in the patients with
(n=5)
control
(n=5)
control
DH
(mean 39.4 ± 43.5; range 1.1–93.81 pg/
(n=5)
(n=5)
ml)
tended to be increased in comparison
Fig. 1. Increased serum levels of cytokines IL-4 and IL-5 in patients with fibrillar-
with the control subjects (mean, 0.26 ± 0.59
type DH. Values are shown as mean ± standard deviation. *p < 0.005; **p < 0.001.
doi: 10.2340/00015555-2604
Acta Derm Venereol 2017; 97: 642–643
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