Acta Dermato-Venereologica issue 50:1 98-1CompleteContent | Page 45
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Dermatofibrosarcoma Protuberans Presenting as a Large Atrophic Plaque on the Chest
Ryosuke SAIGUSA, Takuya MIYAGAWA*, Satoshi TOYAMA, Jun OMATSU, Tomomitsu MIYAGAKI, Yuri MASUI, Daisuke
YAMADA and Shinichi SATO
Department of Dermatology, University of Tokyo Graduate School of Medicine, 7-3-1 Hongo, Bunkyo-ku, Tokyo, 113-8655, Japan. *E-mail:
[email protected]
Accepted Sep 19, 2017; Epub ahead of print Sep 20, 2017
Atrophic dermatofibrosarcoma protuberans (DFSP) is a
very rare variant of DFSP, which presents as an atrophic,
asymptomatic plaque that can be difficult to diagnose.
Like classic DFSP, standard wide excision is necessary
for the treatment of atrophic DFSP, thus accurate diag-
nosis is indispensable. We report here a case of atrophic
DFSP that presented as an unprecedentedly large atrophic
plaque on the anterior chest, which was diagnosed and
treated successfully.
CASE REPORT
A 48-year-old healthy Japanese woman presented with an
8-year history of red nodules surrounded by a palm-sized
(13×12 cm) area of red atrophic plaque on the anterior
chest wall (Fig. 1). She had no history of surgery or
trauma to the chest. She had noticed the atrophic plaque at
the age of 40 years. The plaque expanded gradually, fol-
lowed by development of red nodules. The results of la-
boratory investigations, including anti-nuclear antibody,
were within normal limits. Histological analysis showed
an extensive basophilic nodular area in the dermis and
upper hypodermis in addition to dermal and epidermal
atrophy (Fig. 2A). This nodular area was composed of
SHORT COMMUNICATION
Fig. 1. A palm-sized red atrophic plaque with red nodules on the
anterior chest.
monomorphic spindle cells with minimal cellular atypia,
which were arranged in a characteristic storiform pattern
(Fig. 2B). Immunohistochemical staining revealed that
these spindle cells stained positively for CD34 (Fig. 2C)
and negatively for S100 protein or epithelial membrane
antigen (EMA), which suggested a diagnosis of DFSP,
plaque-like CD34-positive dermal fibroma or solitary
fibrous tumour. To confirm the diagnosis, we further
Fig. 2. Histopathology, immunostaining and molecular analysis. (A,
B) Haematoxylin-eosin staining of the atrophic plaque lesion (A, ×12.5; B,
×400). (C) CD34 immunostaining of the atrophic lesion (×400). (D) The
detection of COL1A1–PDGFB gene fusion transcripts in the skin samples
from the lesion.
This is an open access article under the CC BY-NC license. www.medicaljournals.se/acta
Journal Compilation © 2018 Acta Dermato-Venereologica.
doi: 10.2340/00015555-2800
Acta Derm Venereol 2018; 98: 155–156